Recurrent Facial Erythema with Burning Sensation and Increased Temperature: A Variant of Erythromelalgia or a New Entity?

Objective Erythromelalgia is a rare clinical syndrome characterized by episodic attacks of burning pain, erythema, and increased temperature, primarily affecting the extremities, and in rare instances, involving the ear, face, neck, and the scrotum. The dermatoscopic features of erythromelalgia in a...

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Published inPain medicine (Malden, Mass.) Vol. 15; no. 6; pp. 1007 - 1010
Main Authors Luo, Di‐Qing, Zhao, Yu‐Kun, Xu, Qing‐Fang, He, Xiang‐Qun, Wu, Liang‐Cai
Format Journal Article
LanguageEnglish
Published England Oxford University Press 01.06.2014
Subjects
Adolescent
Dermatoscope
Erythema - complications
Erythema - diagnosis
Erythermalgia
Erythromelalgia
Erythromelalgia - complications
Erythromelalgia - diagnosis
Face
Facial Pain - complications
Facial Pain - diagnosis
Female
Humans
Pain
Pain - complications
Pain - diagnosis
Recurrence
Temperature
Treatment
Dermatoscope
Erythromelalgia
Pain
Treatment
Erythermalgia
Face
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Summary:Objective Erythromelalgia is a rare clinical syndrome characterized by episodic attacks of burning pain, erythema, and increased temperature, primarily affecting the extremities, and in rare instances, involving the ear, face, neck, and the scrotum. The dermatoscopic features of erythromelalgia in a case with solely facial involvement have never been described previously. Observations We describe a 14‐year‐old female who presented with erythema, burning sensation, and warmth on her face only, which mimic the features of erythromelalgia. Physical examination showed higher temperature on the involved cheeks than on axillas during the episode, while the temperature on both areas was the same between episodes. Dermatoscope showed more dilated vessels inside the erythema during the episodes than between the episodes. The symptoms had excellent response to the combination treatment of gabapentin, indomethacin, and topical lidocaine compounds. Conclusions The present case is considered to be a variant of erythromelalgia. Its erythema may be resulted from the dilated vessels. Combination of modalities may provide effective management for erythromelalgia. “Erythermalgia” may be better than “erythromelalgia” to describe such conditions.
Bibliography:ObjectType-Case Study-2
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ISSN:1526-2375
1526-4637
DOI:10.1111/pme.12343