Resection of a cardiac aneurysm in an infant with anomalous origin of the left coronary artery from the pulmonary trunk

• Published in: Cardiology in the young Vol. 14; no. 1; pp. 106 - 108
• Main Authors: Grotenhuis, Heynric B., Backx, Ad, Nijveld, Aagje
• Format: Journal Article
• Language: English
• Published: Cambridge, UK Cambridge University Press 01.02.2004
• Subjects: ALCAPA; Bland-White-Garland syndrome; Brief Report; cardiac aneurysm; Coronary Vessel Anomalies - complications; Female; Heart Aneurysm - etiology; Heart Aneurysm - surgery; Hospitals; Humans; infancy; Infant, Newborn; Infant, Premature; Intensive care; Myocardial Ischemia - etiology; Physical examinations; Postoperative period; Pulmonary Artery - abnormalities; Treatment Outcome; Veins & arteries; Ventilation; Bland-White-Garland syndrome; infancy; ALCAPA; cardiac aneurysm
• ISSN: 1047-9511; 1467-1107
• DOI: 10.1017/S1047951104001222

We describe an infant with an anomalous left coronary artery arising from the pulmonary trunk leading to myocardial ischaemia and development of an apical aneurysm of the left ventricle. Clinical presentation in general is based on myocardial hypoperfusion resulting in ischaemia and infarction. When presenting in infancy, however, then the features, as in our patient, may be tachypnea, dyspnea, failure to thrive and irritability, especially during feeding. Then, again as in our patient, it is possible to miss the definitive diagnosis, which is made by echocardiography and cardiac catheterization. Reimplantation of the anomalous left coronary artery into the aorta usually results in improvement of left ventricular function over time. In our patient, the myocardial infarction was complicated by formation of an aneurysm, and reimplantation alone was not sufficient to restore cardiac function. Resection of the aneurysm greatly improved the hemodynamics.